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2020, Number 1

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Rev Odont Mex 2020; 24 (1)

Acquired lymphangiectasia of lower lip. A clinical case report

Flores FDA, Rumayor PA, Vértiz FK, Galindo RM, Esparza DSC, Iñigo BA

Language: Spanish
References: 14
Page: 66-71
PDF size: 141.50 Kb.


ABSTRACT

Background: The best-known pathology of lymphatic vessels is lymphangioma, which is considered a developmental malformation rather than a true neoplasia. Oral lymphangiomas are more common in children with half of the cases affecting tongue as clusters of translucent vesicles. However, single, circumscribed, and superficial lesions may appear intraorally. They are considered as focal ectasia of lymph vessels, known as lymphangiectasia, and can be secondary to obstruction or trauma. Objective: The goal of this report is to present a case of a lower lip superficial acquired lymphangiectasia and to compare the differential diagnoses on the basis of the clinical presentation. Case presentation: A six-year-old girl presented with an asymptomatic lower lip lesion. On examination two translucent and fluctuant small nodules were observed in lower labial mucosa. The first clinical diagnostic hypothesis was mucocele. Under local anesthesia, an excisional biopsy of both lesions was performed. A histopathological study revealed a superficial ectatic vascular space, lined by endothelium. Immunohistochemistry with D2-40 confirmed its lymphatic nature. After eight months of follow-up, the patient is well and shows no recurrence. Conclusions: This clinical case is an example of an acquired lymphangiectasia probably secondary to trauma to peripheral lymphatic capillaries caused by the use of a mandibular removable space maintainer. This entity is different from the deep diffuse lymphangiomas which are true vascular malformations and are generally present since birth. In oral mucosa, most lymphatic lesions are superficially located and most commonly represent lymphangiectasias and not true lymphangiomas.


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