medigraphic.com
ISSN 2078-7170 (Electronic)

2020, Number 4

<< Back Next >>

CorSalud 2020; 12 (4)

Cor triatriatum sinister, a classic but somewhat forgotten anomaly: Apropos of a case

Antunes VMB, Ravelo DR, de Lima DLM, Tavares MT, Méndez PTC, Da Costa MHA

Language: Spanish
References: 21
Page: 445-450
PDF size: 623.18 Kb.


ABSTRACT

A heart with three atria, totaling five chambers in all, was a fact that surprised medicine more than a century ago. This rare congenital heart defect has a very low incidence, which makes it very little known to the young generations of doctors dedicated to cardiovascular diseases. The cor triatriatum sinister is usually diagnosed in early childhood, and it is considered a congenital cause of mitral stenosis. Surgical approach is the choice to release the obstacle in order to adequate blood flow through the left atrium. We present the case of a young adult with typical symptoms of mitral stenosis, without apparent key elements on the physical examination and that the echocardiogram showed this anomaly, hardly seen and published in our field in adult patients.


REFERENCES

  1. Chelo D, Nguefack F, Menanga AP, Ngo Um S, Gody JC, Tatah SA, et al. Spectrum of heart diseases in children: an echocardiographic study of 1,666 subjects in a pediatric hospital, Yaounde, Cameroon. Cardiovasc Diagn Ther. 2016;6(1):10-9.

  2. Bannerman CH, Mahalu W. Congenital heart disease in Zimbabwean children. Ann Trop Paediatr. 1998;18(1):5-12.

  3. Manuel V, Morais H, Manuel A, David B, Gamboa S. Ventricular septal defect in children and adolescents in Angola: experience of a tertiary center. Rev Port Cardiol. 2014;33(10):637-40.

  4. Ijuin S, Tobe S, Sugiyama H, Nosho H, Hayashi T, Yamaguchi M, et al. Cor triatriatum diagnosed in adulthood; Report of a Case]. Kyobu Geka. 2015;68(7):532-4.

  5. Church WS. Congenital malformation of heart: abnormal septum in left auricle. Trans Path Soc Lond 1868;19:188-90.

  6. Jha AK, Makhija N. Cor Triatriatum: A Review. Semin Cardiothorac Vasc Anesth. 2017;21(2):178-85.

  7. Loeffler E. Unusual malformation of the left atrium; pulmonary sinus. Arch Pathol. 1949;48(5):371-6.

  8. Ullah W, Sattar Y, Rauf H, Roomi S, Shah MI. A systematic review of a long-forgotten cause of atrial fibrillation and stroke: Cor Triatriatum. Cureus [Internet]. 2019 [citado 1/03/2020];11(12):e6371. Disponible en: https://doi.org/10.7759/cureus.6371

  9. Fuchs MM, Connolly HM, Said SM, Egbe AC. Outcomes in patients with cor triatriatum sinister. Congenit Heart Dis. 2018;13(4):628-32.

  10. Elagizi A, Marvin R, O'Bryan G, Vyas V, Arcement L. Three's a Crowd - An Extremely Rare Case of Cor Triatriatum Dexter. J La State Med Soc. 2017;169(2):50-1.

  11. Raheja H, Namana V, Moskovits N, Hollander G, Shani J. Cor Triatriatum Sinistrum. Arq Bras Cardiol. 2018;110(1):101.

  12. Narayanapillai J. Cor triatriatum sinister with severe obstruction: a rare presentation in an adult. BMJ Case Rep [Internet]. 2016 [citado 3/03/2020];2016:bcr2016215718. Disponible en: http://dx.doi.org/10.1136/bcr-2016-215718

  13. Aje A, Adebayo O, Towoju O, Oni O, Adeoye AM, Ogah OS, et al. Cor triatriatum sinistrum in a Nigerian adult. Niger J Cardiol. 2016;13(2):140-3.

  14. Ker J. Cor triatriatum sinister presenting with adult onset atrial fibrillation--another rare cause for a common clinical problem. Int J Cardiol [Internet]. 2013 [citado 3/03/2020];167(1):e12-3. Disponible en: https://doi.org/10.1016/j.ijcard.2013.01.269

  15. Ather B, Meredith A, Siddiqui WJ. Cor Triatriatum. [Internet]. Treasure Island (FL): StatPearls Publishing [citado 3/03/2020]; 2020. Disponible en: https://www.ncbi.nlm.nih.gov/books/NBK534243/?report=printable

  16. Bejiqi R, Retkoceri R, Bejiqi H, Zeka N, Kelmendi M. Echocardiographic diagnosis of divided right atrium-cor triatriatum dextrum. Med Arh. 2010;64(5):303-4.

  17. Holloway BJ, Agarwal PP. Incidental cor triatriatum discovered on multidetector computed tomography. J Thorac Imaging. 2011;26(2):W45-7.

  18. Kacenelenbogen R, Decoodt P. Biplane transesophageal echocardiographic diagnosis of cor triatriatum. Chest. 1994;105(2):601-2.

  19. Ozyuksel A, Yildirim O, Avsar M, Hayirlioglu M, Demiroluk S, Kucukosmanoglu O, et al. Surgical correction of cor triatriatum sinister in the paediatric population: mid-term results in 15 cases. Eur J Cardiothorac Surg. 2015;47(1):e25-8.

  20. Saxena P, Burkhart HM, Schaff HV, Daly R, Joyce LD, Dearani JA. Surgical repair of cor triatriatum sinister: the Mayo Clinic 50-year experience. Ann Thorac Surg. 2014;97(5):1659-63.

  21. Li WW, Koolbergen DR, Bouma BJ, Hazekamp MG, de Mol BA, de Winter RJ. Cathether-based interventional strategies for cor triatriatum in the adult - feasibility study through a hybrid approach. BMC Cardiovasc Disord [Internet]. 2015 [citado 4/03/2020];15:68. Disponible en: https://doi.org/10.1186/s12872-015-0067-4




2020     |     www.medigraphic.com